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Risk of intestinal involvement in mucocutaneous-onset Behçet’s disease: data from the AIDA network registry

  • Antonio Vitale
  • , Valeria Caggiano
  • , Jessica Sbalchiero
  • , Francesco Gavioli
  • , Giuseppe Lopalco
  • , Gaafar Ragab
  • , Silvana Guerriero
  • , Ibrahim Almaglouth
  • , Abdurrahman Tufan
  • , Roberto Giacomelli
  • , Haner Direskeneli
  • , Piero Ruscitti
  • , Gülen Hatemi
  • , Francesco Carubbi
  • , Ezgi Deniz Batu
  • , Seza Ozen
  • , Jurgen Sota
  • , Henrique Ayres Mayrink Giardini
  • , Micol Frassi
  • , Petros P. Sfikakis
  • Maria Morrone, Federica Gatti, Amina Maher, Ayman Abdel Monem Ahmed Mahmoud, Rosanna Dammacco, Hamit Kucuk, Riza Can Kardas, Ibrahim Yahya Cakir, Letizia Pia di Corcia, Fatma Alibaz Öner, Gizem Sevik, Martina Gentile, Alican Karakoc, Alessia Alunno, Hulya Ercan Emreol, Francesca Crisafulli, Maria Tektonidou, Francesco Ciccia, Maissa Thabet, Serena Bugatti, Alessandra Milanesi, Maria Sole Chimenti, Benedetta Monosi, Matteo Piga, Alberto Floris, Andrea Hinojosa-Azaola, Guillermo Arturo Guaracha-Basañez, Cecilia Beatrice Chighizola, José Hernández-Rodríguez, Marco Cattalini, Marcello Govoni, Ombretta Viapiana, Adele Civino, Daniela Opris-Belinski, Carla Gaggiano, Rosaria Talarico, Annarita Giardina, Giacomo Emmi, Piercarlo Sarzi Puttini, Maria Cristina Maggio, Paola Parronchi, Piero Portincasa, Alejandra de-la-Torre, Juanita Cardona-López, Stefano Gentileschi, Angela Mauro, Gian Domenico Sebastiani, Maria Francesca Gicchino, Ali Şahin, Donato Rigante, Emre Bilgin, Emanuela Del Giudice, Luciana Breda, Amato De Paulis, Alberto Lo Gullo, Şükran Erten, Samar Tharwat, Lampros Fotis, Maier Armin, Antonella Insalaco, Anastasios Karamanakos, Alessandro Conforti, Özgül Soysal Gündüz, Abdelhfeez Moshrif, Francesca Li Gobbi, Stefania Costi, Elena Bartoloni, Patrizia Barone, Serena Guiducci, Andrés González-García, Inés Hernanz Rodriguez, Giovanni Conti, Annamaria Iagnocco, Fatos Önen, Sulaiman M. Al-Mayouf, Ali İbrahim Hatemi, Alberto Balistreri, Claudia Fabiani, Luca Cantarini

Producción científica: Contribución a revistaArtículo de Investigaciónrevisión exhaustiva

Resumen

Objective – Behçet’s disease (BD) may initially manifest solely with mucocutaneous involvement. This study aimed to identify demographic and clinical factors associated with subsequent intestinal involvement in patients presenting exclusively with mucocutaneous manifestations during early disease stages. Methods – Data were obtained from the International AutoInflammatory Disease Alliance Network registry dedicated to BD; a Bayesian statistical approach was employed to address the limited sample size resulting from subgroup stratifications. Results – In total, 328 BD patients with exclusively mucocutaneous onset were enrolled; of these, 46 (14%) developed intestinal involvement over time. The risk of ocular involvement was higher among patients with intestinal manifestations (OR: 3.02, 95% CrI: 1.24–6.08; posterior probability: 99.3%). Minor aphthous ulcers without major aphthosis were protective towards intestinal involvement (OR: 0.47, 95% CrI: 0.22–0.98; posterior probability: 97.98%). Conversely, major aphthous ulcers increased the risk (OR: 3.25, 95% CrI: 1.50–7.02; posterior probability: 99.7%), along with the combination of oral major aphthosis with: i) genital aphthosis (OR = 2.77, 95%CrI: 1.14-6.58; posterior probability: 98.45%); ii) pseudofolliculitis (OR = 3.18, 95%CrI: 1.15-8.33; posterior probability: 98.72%); iii) genital aphthosis plus pseudofolliculitis (OR = 5.22, 95%CrI: 1.71-16.35; posterior probability of 99.77%). Pseudofolliculitis plus cutaneous manifestations other than erythema nodosum were protective against intestinal involvement (OR = 0.01, 95%CrI: 0.0-0.98; posterior probability: 97.55%). Conclusion – Major aphthosis was the strongest factor associated with intestinal involvement in BD patients initially presenting with mucocutaneous symptoms only. In such patients, intestinal involvement correlated with increased risk of ocular inflammation.

Idioma originalInglés estadounidense
Número de artículo1778171
PublicaciónFrontiers in Immunology
Volumen17
DOI
EstadoPublicada - may 13 2026

Áreas temáticas de ASJC Scopus

  • Inmulogía y alergología
  • Inmunología

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